Rarer Components of a Rare Disease: Accessory Hemidiaphragm and Horseshoe Lung with Scimitar Syndrome: Two Case Reports

Ozgur I. Koska; Hüdaver Alper

doi:10.2174/1573405619666230322104945

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oa Rarer Components of a Rare Disease: Accessory Hemidiaphragm and Horseshoe Lung with Scimitar Syndrome: Two Case Reports
Authors: Ozgur I. Koska¹ and Hüdaver Alper²
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Affiliations: ¹ Biomedical Imaging Department, Dokuz Eylül University, Kuruçeşme 35390, Buca İzmir, Turkey ² Radiology Department, Ege Üniversitesi Tıp Fakültesi Hastanesi, Buca İzmir, Turkey
Source: , Volume 20, Issue 1, Jan 2024, e220323214859
DOI: https://doi.org/10.2174/1573405619666230322104945
- Received: 08 Sep 2022
- Accepted: 24 Jan 2023
- Available online: 04 May 2023

Abstract

Introduction:

Scimitar syndrome is a rare developmental anomaly with an incidence of 2/100.000 births. Major components of this disease are partial anomalous pulmonary venous drainage, pulmonary hypoplasia, systemic arterialization of the right basal lung, and dextroposition of the heart. Horseshoe lung and accessory hemidiaphragm are two rarer components of this disease.

Case Presentation:

In this paper, horseshoe lung and accessory diaphragm associated with Scimitar syndrome have been reported in two cases.

Conclusion:

In conclusion, being aware of rare manifestations of rare diseases is important to fully describe the pathologic spectrum of the disease. This will assist in better management and decision-making process.

This is an open access article distributed under the terms of the Creative Commons Attribution 4.0 International Public License (CC-BY 4.0), a copy of which is available at: https://creativecommons.org/licenses/by/4.0/legalcode. This license permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.

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2025-01-10

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/content/journals/cmim/10.2174/1573405619666230322104945

Rarer Components of a Rare Disease: Accessory Hemidiaphragm and Horseshoe Lung with Scimitar Syndrome: Two Case Reports

20, e220323214859 (2024); https://doi.org/10.2174/1573405619666230322104945

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Article Type: Case Report

Keyword(s): Accessory hemidiaphragm; Case report; Horseshoe lung; Pulmonary hypoplasia; Scimitar syndrome

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oa Rarer Components of a Rare Disease: Accessory Hemidiaphragm and Horseshoe Lung with Scimitar Syndrome: Two Case Reports

Abstract

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